Congenital megalourethra is a rare mesenchymal anamoly of the male urethra. It is defined as dilation of the anterior urethra due to absence of development or deficiency of erectile tissue of the penis. It leads to deformity of the penis (scaphoid megalourethra) or impotence (fusiform megalourethra) and also renal insufficiency and pulmonary hypoplasia. The associated anomalies are often life threatening and influence the management and prognosis. We present here a report of a case of megalourethra.